Phenotypic variability of the kyphoscoliotic type of Ehlers-Danlos syndrome (EDS VIA): clinical, molecular and biochemical delineation
2011

Understanding Ehlers-Danlos Syndrome Type VIA

Sample size: 15 publication 10 minutes Evidence: moderate

Author Information

Author(s): Marianne Rohrbach, Anthony Vandersteen, Uluç Yiş, Gul Serdaroglu, Esra Ataman, Maya Chopra, Sixto Garcia, Kristi Jones, Ariana Kariminejad, Marius Kraenzlin, Carlo Marcelis, Matthias Baumgartner, Cecilia Giunta

Primary Institution: University Children's Hospital and Children's Research Centre, Zurich, Switzerland

Hypothesis

The study aims to characterize the clinical, molecular, and biochemical features of the kyphoscoliotic type of Ehlers-Danlos syndrome (EDS VIA).

Conclusion

EDS VIA is a highly variable condition that can present with a wide range of symptoms, including cognitive delays and increased risk of vascular events.

Supporting Evidence

  • The study identified a broad spectrum of clinical features in patients with EDS VIA.
  • Significant variability in the age of diagnosis and severity of symptoms was observed.
  • Urinary pyridinoline cross-links were found to be a reliable diagnostic test for EDS VIA.
  • Five patients exhibited developmental delays, which is not typically associated with EDS VIA.

Takeaway

EDS VIA is a rare disease that affects how the body makes collagen, leading to problems like weak muscles and flexible joints. Some kids with this condition might also have trouble learning.

Methodology

The study involved clinical, biochemical, and molecular characterization of 15 newly diagnosed patients with EDS VIA.

Potential Biases

Potential bias may arise from the reliance on clinical diagnosis and the variability in patient reporting.

Limitations

The study is limited by the small sample size and the variability in clinical presentation among patients.

Participant Demographics

Participants included 53% males and 47% females, with a majority from Turkey, former Yugoslavia, and the Middle East.

Statistical Information

P-Value

0.02

Statistical Significance

p<0.05

Digital Object Identifier (DOI)

10.1186/1750-1172-6-46

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