A novel UBA1 gene mutation in a patient with infantile respiratory distress syndrome
2025

A new UBA1 gene mutation linked to infantile respiratory distress syndrome

Sample size: 1 publication Evidence: moderate

Author Information

Author(s): Miyata Masafumi, Kojima Arisa, Kawai Yuri, Uchida Hidetoshi, Boda Hiroko, Ishihara Naoko, Inagaki Hidehito, Yoshikawa Tetsushi, Kurahashi Hiroki

Primary Institution: Fujita Health University School of Medicine

Hypothesis

Is there a novel mutation in the UBA1 gene associated with infantile respiratory distress syndrome?

Conclusion

The study identified a de novo mutation in the UBA1 gene that may be linked to the patient's respiratory and neuromuscular symptoms.

Supporting Evidence

  • The patient was diagnosed with respiratory distress syndrome and treated with surfactant.
  • A de novo hemizygous mutation in the UBA1 gene was identified.
  • The mutation was located in a known hotspot for related diseases.

Takeaway

A baby with breathing problems had a new mutation in a gene that might explain his health issues.

Methodology

Targeted exome sequencing was performed to identify mutations in disease-associated genes.

Limitations

The study is based on a single case report, limiting the generalizability of the findings.

Participant Demographics

{"gender":"male","birth_weight":2890,"birth_height":47,"birth_head_circumference":34,"parents_age":{"mother":30,"father":26},"sibling_health":"sister had B-cell precursor lymphoblastic leukemia"}

Digital Object Identifier (DOI)

10.1038/s41439-024-00307-7

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