The gene coding for PGC-1α modifies age at onset in Huntington's Disease
2009

PGC-1α Gene and Huntington's Disease Onset

Sample size: 447 publication Evidence: moderate

Author Information

Author(s): Weydt Patrick, Soyal Selma M, Gellera Cinzia, DiDonato Stefano, Weidinger Claus, Oberkofler Hannes, Landwehrmeyer G Bernhard, Patsch Wolfgang

Hypothesis

PPARGC1A polymorphisms are associated with the age at onset in Huntington's disease patients.

Conclusion

The study found that certain haplotypes of the PGC-1α gene are associated with a delay in the onset of Huntington's disease symptoms.

Supporting Evidence

  • Homozygosity for the 'protective' block 2 haplotype was associated with a significant delay in disease onset.
  • The mean age at onset was 48.9 years among the participants.
  • The study identified two haplotype blocks in the PPARGC1A gene that influence age at onset.

Takeaway

This study shows that a specific gene can affect how early people get sick with Huntington's disease.

Methodology

The study analyzed genetic data from 447 unrelated Huntington's disease patients to assess the association between PGC-1α haplotypes and age at onset.

Limitations

The study is limited to a specific population and may not generalize to all Huntington's disease patients.

Participant Demographics

The cohort included 215 male and 234 female unrelated HD patients.

Statistical Information

P-Value

0.0025

Statistical Significance

p<0.05

Digital Object Identifier (DOI)

10.1186/1750-1326-4-3

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