Submicroscopic chromosome imbalance in patients with developmental delay and/or dysmorphism referred specifically for Fragile X testing and karyotype analysis
2008

Chromosome Imbalance in Patients with Developmental Delay

Sample size: 403 publication Evidence: moderate

Author Information

Author(s): Ahn Joo Wook, Mann Kathy, Docherty Zoe, Mackie Ogilvie Caroline

Primary Institution: Guy's and St Thomas' NHS Foundation Trust, London, UK

Hypothesis

What is the prevalence of submicroscopic chromosome imbalances in patients with developmental delay and/or dysmorphism referred for Fragile X testing?

Conclusion

Karyotype analysis combined with MLPA assays for subtelomeres and microdeletion loci may improve diagnostic yield in this patient group.

Supporting Evidence

  • The overall abnormality detection rate was 2.5% for karyotype analysis and 7.2% for MLPA testing.
  • 5.5% of subtelomere tests and 2.1% of microdeletion tests gave abnormal results.
  • None of the patients was found to have a Fragile X expansion.

Takeaway

Doctors looked at the chromosomes of kids with developmental delays to find hidden problems. They found some issues that regular tests missed.

Methodology

Patients were tested using Multiplex Ligation-dependent Probe Amplification (MLPA) for chromosome imbalances.

Limitations

Parental samples were not available for all cases, limiting inheritance studies.

Participant Demographics

Patients referred for karyotyping and Fragile X testing due to developmental delay and/or dysmorphism.

Digital Object Identifier (DOI)

10.1186/1755-8166-1-2

Want to read the original?

Access the complete publication on the publisher's website

View Original Publication